DOI: http://dx.doi.org/10.18203/issn.2455-4510.IntJResOrthop20210636

Congenital pseudarthrosis of the clavicle in an adult: case report and literature review

Sara Elisa Diniz, Manuel Fernandes Marques, Luís Barros, Rui Claro

Abstract


A 27 years old male, presented with a bump over the middle third of is right clavicle and a foreshortened shoulder girdle causing a severe deformity. Radiographs revealed a Congenital pseudarthrosis of the clavicle (CPC). A resection of the pseudarthrosis was carried and internal fixation with a reconstruction plate was done using iliac graft. One year after he was asymptomatic, without any functional impairment and very satisfied with the final cosmetic result. There is no consensus about optimal treatment. We present a rare case of surgical in an adult patient, and demonstrate why treatment must be individualized and surgical associated complications must be discussed.


Keywords


Pseudoarthrosis, Clavicle, Childhood, Congenital, Adult

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References


Fitzwilliams DCL. Hereditary cranio-cleido-dysostosis. Lancet. 1910;2:1466-75.

Abdellaoui H, Atarraf K, Chater L, Afifi MA. Congenital pseudarthrosis of the clavicle treated by Masquelet technique. BMJ Case Reports. 2017;221557.

Di Gennaro GL, Cravino M, Martinelli A, Berardi E, Rao A, Stilli S, et al. Congenital pseudarthrosis of the clavicle: a report on 27 cases. J Shoulder Elbow Surg. 2017;26(3):65-70.

Chalfant JS, Sanchez TR. Congenital Clavicular Pseudoarthosis - How to Differentiate It From the More Common Clavicular Fractures. Pediatric Emergency Care. 2017;1.

Galanopoulos I, Ashwood N, Garlapati AK, Fogg Q. Congenital pseudarthrosis of clavicle: illustrated operative technique and histological findings. Case Reports. 2012;20(1).

Lloyd-Roberts GC, Apley AG, Owen R. Reflections about aetiology of congenital pseudarthrosis of clavicle. With a note on cranio-cleido dysostosis. J Bone Joint Surg Br. 1975;57:24-9.

Gibson DA, Carrol N. Congenital Pseudoarthrosis of the clavicle. J Bone Joint Surg. 1970;52:629-43.

Ogata S, Uhthoff HK. The early development and ossification of the human clavicle - an embryologic study. Acta Orthop Scand. 1990;61:330-4.

Ettl V, Wild A, Krauspe E, Raab P. Surgical treatment of congenital pseudoarthrosis of the clavicle: A report of three cases and review of the literature. Eur J Pediatr Surg. 2005;15:56-60.

Kim AE, Vuillermin CB, Bae DS, Samora JB, Waters PM, Bauer AS. Congenital pseudarthrosis of the clavicle: surgical decision making and outcomes. J Shoulder Elbow Surg. 2019.

Figueiredo MJPSS, Braga SR , Akkari M, Prado JCL, Santili C. Congenital Pseudarhtrosis of the clavicle. Rev Bras Ortop. 2012;47(1):21-6

Sales de Gauzy J, Baunin C, Puget C. Congenital pseudarthrosis of the clavicle and thoracic outlet syndrome in adolescence. J Pediatr Orthop B. 1999;8(4):299-301.

Sung THT, Man EMW, Chan ATS, Lee WK. Congenital pseudarthrosis of the clavicle: a rare and challenging diagnosis. Hong Kong Med. 2013;19(3):265-7.

Watson HI, Hopper GP, Kovacs P. Congenital pseudarthrosis of the clavicle causing thoracic outlet syndrome. Case Reports. 2013;bcr2013010437.

Studer K, Baker MP, Krieg AH. Operative treatment of congenital pseudarthrosis of the clavicle. J Pediatric Orthopaedics B. 2017;26(3):245-9.

Giwnewer U, Rubin G, Dohovni E, Rozen N, Bor N. Congenital pseudoarthrosis of the clavicle: Should we reconsider timing and fixation method? J Orthopaedic Surg. 2018;26(3):230949901879953.

Persiani P, Molayem I, Villani C, Cadilhac C, Glorion C. Surgical treatment of congenital pseudarthrosis of the clavicle: a report on 17 cases. Acta Orthop Belg. 2008;74:161-6.

Toledo LC, MacEwen GD. Severe complication of surgical treatment of congenital pseudarthrosis of the clavicle. Clin Orthop Relat Res. 1979;139:64-7.

Grogan DP, Love SM, Guidera KJ, Ogden JA. Operative treatment of congenital pseudarthrosis of the clavicle. J Pediatr Orthop B. 1991;11:176-80.

Chandran P, George H, James LA. Congenital clavicular pseudarthrosis: comparison of two treatment methods. J Children’s Orthopaedics. 2011;5(1):1-4.

Molto LFJ, Lluch BDJ, Garrido IM. Congenital pseudarthrosis of the clavicle: a proposal for early surgical treatment. J Pediatr Orthop. 2001;21(5):689-93

Dzupa V, Bartonicek J, Zidka M. Fracture of the clavicle after surgical treatment for congenital pseudarthrosis. Med Sci Monit. 2004;10(1):CS1-4.

Shalom A, Khermosh O, Wientroub S. The natural history of congenital pseuadarthrosis of the clavicle. J Bone Joint Surg Br. 1994;76B:846-7.